{Reference Type}: Case Reports {Title}: Dural sinus malformation presenting with proptosis: report and review of a rare entity. {Author}: Rao TMN;Thakar S;Pandey P;Aryan S; {Journal}: Childs Nerv Syst {Volume}: 40 {Issue}: 8 {Year}: 2024 Aug 22 {Factor}: 1.532 {DOI}: 10.1007/s00381-024-06410-y {Abstract}: Dural sinus malformation (DSM) is a rare vascular malformation characterized by the dilatation of a dural venous sinus with or without an anomalous jugular bulb. Its presentation with venous-reflux-related secondary proptosis is anecdotal, with only six such cases reported so far. We report a 17-month-old boy who presented with a progressive proptosis of the right eye secondary to a DSM of the transverse sinus and torcula. Following endovascular embolization of the arterio-venous fistula, complete thrombosis of the venous lake and improvement in proptosis was noted at 6-month follow-up. Prognosis of this rare malformation is variable and dependent on specific angio-architectural features.