%0 Case Reports %T A case of reverse amblyopia in a myopic anisometropic patient: an atypical presentation. %A AlTurki H %A Amir A %A AlShamlan F %A Emara K %A AlSahaf E %A Altaf H %J J Surg Case Rep %V 2024 %N 5 %D 2024 May %M 38784199 暂无%R 10.1093/jscr/rjae320 %X We herein report a case of a 4-year-old female patient who presented with anisometropic amblyopia with initial visual acuity recorded at 20/400 OD and 20/100 OS. The patient was recommended for patching. Eighteen months later, the patient presented with visual acuity of 20/60 OD and 20/80 and reverse amblyopia was noted. In settings of amblyopia, where alternate patching may be used, it is most likely that reverse amblyopia, if present, will affect the more myopic eye. However, unexpectedly, in this case, reverse amblyopia occurred in the less myopic eye. With discontinuation of occlusion therapy and continued use of optical correction, the patients reverse amblyopia resolved and the visual equity equalized. To our knowledge, this is the first case described in the literature demonstrating such an occurrence. Awareness of this rare presentation by clinicians is of great importance to aid in correctly diagnosing and treating such patients.