关键词: A case report Acute acquired comitant esotropia Hydrocephalus Lhermitte–Duclos disease Papilledema

Mesh : Humans Female Esotropia / etiology diagnosis Adolescent Magnetic Resonance Imaging Hamartoma Syndrome, Multiple / complications diagnosis surgery Cerebellar Neoplasms / complications surgery Acute Disease Diplopia / etiology Papilledema / etiology diagnosis

来  源:   DOI:10.1186/s13256-024-04683-0   PDF(Pubmed)

Abstract:
BACKGROUND: Acute acquired comitant esotropia caused by prolonged near work, such as the use of digital devices, has been frequently reported in recent years. However, intracranial examination is necessary even for patients with nonparalytic comitant esotropia. Lhermitte-Duclos disease is a rare tumor that grows in layers in the cerebellum. Among those with this disease, cases of esotropia have been reported due to abduction limitation of the eye, but there have been no reports of comitant esotropia. Here, we report the case of a young woman with acute acquired comitant esotropia who was found to have Lhermitte-Duclos disease.
METHODS: A 16-year-old Japanese female patient, whose ethnicity was Asian, was referred to our hospital for acute acquired comitant esotropia. Fundus examination revealed papilledema in both eyes, and magnetic resonance imaging of the head revealed a cerebellar tumor in the right cerebellum with obstructive hydrocephalus. She underwent partial tumor resection, and a histopathological diagnosis of Lhermitte-Duclos disease was obtained. However, comitant esotropia status remained unchanged, and she underwent strabismus surgery. Finally, diplopia disappeared completely.
CONCLUSIONS: Neurological and intracranial imaging examinations are essential when acute acquired comitant esotropia is observed. Acute acquired comitant esotropia by Lhermitte-Duclos disease did not improve with partial tumor resection and required strabismus surgery, but good surgical results were obtained.
摘要:
背景:长时间近距离工作引起的急性获得性伴随内斜视,例如使用数字设备,近年来经常有报道。然而,即使对于非麻痹性共同性内斜视患者,颅内检查也是必要的。Lhermitte-Duclos病是一种罕见的肿瘤,在小脑中分层生长。在患有这种疾病的人中,由于眼睛的外展限制,内斜视的病例已被报道,但是没有伴发内斜视的报道。这里,我们报道了一例患有急性获得性共同性内斜视的年轻女性,该女性被发现患有Lhermitte-Duclos病。
方法:一名16岁的日本女性患者,他的种族是亚洲人,因急性获得性共同性内斜视被转诊到我们医院。眼底检查发现双眼有乳头水肿,头部磁共振成像显示右小脑有小脑肿瘤伴梗阻性脑积水。她接受了部分肿瘤切除术,并获得了Lhermitte-Duclos病的组织病理学诊断。然而,伴随的内斜视状态保持不变,她接受了斜视手术.最后,复视完全消失。
结论:当观察到急性获得性共同性内斜视时,神经和颅内影像学检查是必不可少的。Lhermitte-Duclos病的急性获得性伴发内斜视在部分肿瘤切除和需要斜视手术后并未改善,但取得了良好的手术效果。
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