关键词: Case report Odontogenic tumors Oral and maxillofacial surgery Unicystic ameloblastoma

来  源:   DOI:10.1016/j.ijscr.2024.109830   PDF(Pubmed)

Abstract:
BACKGROUND: Unicystic ameloblastomas are a rare variant of ameloblastomas, which are characterized by slow growth and being relatively locally aggressive, with the main site of origin being the posterior portion of the mandible, it also refers to those cystic lesions that show clinical, radiographic, or gross features of a jaw cyst.
METHODS: A 27-year-old female patient presented with a chief complaint of extensive mass of mandible along with severe swelling and numbness of right lips and chin. The oral examination revealed a swelling in the molar region of the right mandible with buccal plate expansion. The radiographic and histopathologic features were consistent with the diagnosis of unicystic ameloblastoma. Consequently, the lesion was surgically removed, and no clinical or radiological recurrence was detected during 5 years post-operative follow-up.
CONCLUSIONS: While previous reports of unicystic ameloblastoma in the posterior portion of the jaw showed favorable prognosis lesions appeared as a unilocular entity, this case reports multilocular appearance and aggressive behavior of expansive unicystic ameloblastoma. Furthermore, while some studies linked the unilocular appearance of unicystic ameloblastoma to impacted tooth, our case suggests a possible traumatic link of preexisting lesion into multilocular unicystic ameloblastoma related to impacted tooth.
CONCLUSIONS: This case presents a rare multilocular unicystic ameloblastoma appearance, notably with impacted tooth involvement. It also indicates the potential transformation of solid ameloblastoma into unicystic ameloblastom.
摘要:
背景:单囊性成釉细胞瘤是一种罕见的成釉细胞瘤,其特点是缓慢的增长和相对局部的侵略性,主要起源是下颌骨的后部,它也指那些显示临床的囊性病变,射线照相,或颌骨囊肿的大体特征。
方法:一名27岁女性患者主诉下颌骨广泛肿块,右唇和下巴严重肿胀和麻木。口腔检查显示右下颌骨磨牙区肿胀,颊板扩张。影像学和组织病理学特征与单囊性成釉细胞瘤的诊断一致。因此,手术切除了病灶,在术后5年随访期间,未发现临床或放射学复发。
结论:虽然先前关于颌骨后部单囊性成釉细胞瘤的报道显示预后良好的病变表现为单眼实体,该病例报告了扩张性单囊性成釉细胞瘤的多房性外观和攻击行为。此外,虽然一些研究将单囊成釉细胞瘤的单眼外观与阻生牙齿联系起来,我们的病例提示先前存在的病变可能与患牙相关的多房单囊性成釉细胞瘤有创伤性联系.
结论:该病例表现为罕见的多房单囊性成釉细胞瘤,尤其是受累的牙齿。它还表明了固体成釉细胞瘤向单囊性成釉细胞的潜在转化。
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