关键词: Fibrous dysplasia Ipsilateral Keratoconus Pediatric Unliteral

来  源:   DOI:10.1016/j.ajoc.2023.101984   PDF(Pubmed)

Abstract:
UNASSIGNED: The purpose of this study is to describe a case of unilateral keratoconus associated with ipsilateral craniofacial fibrous dysplasia and its subsequent management with corneal collagen cross-linking.
UNASSIGNED: This is an interventional case report of a 16-year-old male with a history of polyostotic fibrous dysplasia of the left frontal bone and orbital roof status post partial resection six years prior who presented to the pediatric ophthalmology clinic with progressively blurry vision in the left eye. Refraction in this eye revealed an increase in cylinder by > 3D from his last refraction two years prior. Pentacam corneal tomography confirmed the diagnosis of keratoconus in the left eye. The patient underwent corneal collagen cross-linking in the affected eye. Postoperatively, he experienced marked improvement in corrected visual acuity with scleral contact lenses and maintained stable astigmatism and keratometry values on Pentacam corneal tomography at his most recent visit 12 months postoperatively.
UNASSIGNED: While it is otherwise felt to be a bilateral disease, unilateral keratoconus may present in the context of ipsilateral orbital pathology. Corneal collagen cross-linking may be used to successfully prevent keratoconus progression in the setting of stable orbital pathology.
摘要:
这项研究的目的是描述一例与同侧颅面纤维发育不良相关的单侧圆锥角膜及其随后的角膜胶原蛋白交联处理。
这是一例介入性病例报告,其中一名16岁男性,在部分切除术前6年有左额骨多骨纤维发育不良和眶顶状态病史,他到儿科眼科诊所就诊,左眼视力逐渐模糊。这只眼睛的折射显示,与他两年前的最后一次折射相比,圆柱体增加了>3D。Pentacam角膜断层扫描证实了左眼圆锥角膜的诊断。患者在受影响的眼睛中进行了角膜胶原交联。术后,在术后12个月的最近一次访视中,他使用巩膜隐形眼镜的矫正视力有了显著改善,并且在Pentacam角膜断层扫描中保持了稳定的散光和角膜曲率测量值.
虽然它被认为是一种双侧疾病,单侧圆锥角膜可能存在于同侧眼眶病理的背景下。角膜胶原交联可用于在稳定的眼眶病理背景下成功预防圆锥角膜进展。
公众号